The Journal of Laryngology & Otology

Clinical Records

Metachronous inflammatory myofibroblastic tumour in the temporal bone: case report

B S Goha1 c1, S P Tana2, S Husaina1, I M Rosea3 and L Saima1

a1 Department of Otorhinolaryngology – Head and Neck Surgery, Faculty of Medicine, Universiti Kebangsaan Malaysia, Kuala Lumpur, Malaysia

a2 Department of Radiology, Faculty of Medicine, Universiti Kebangsaan Malaysia, Kuala Lumpur, Malaysia

a3 Department of Pathology, Faculty of Medicine, Universiti Kebangsaan Malaysia, Kuala Lumpur, Malaysia

Abstract

Objective: We report an extremely rare case of metachronous inflammatory myofibroblastic tumour in the temporal bone.

Method: Case report and review of the world literature on metachronous inflammatory myofibroblastic tumour.

Results: Inflammatory myofibroblastic tumour in the temporal bone is rare, and metachronous inflammatory myofibroblastic tumour in the temporal bone has never been reported in the English medical literature. We report a case of inflammatory myofibroblastic tumour in the right temporal bone in a 27-year-old woman presenting with right-sided otalgia and progressive hearing loss. A metachronous lesion was discovered in the left temporal bone one year later. The patient underwent surgical excision of the tumour via canal wall down mastoidectomy for both lesions. Long term steroids were prescribed after both surgical procedures. At follow up three years after the last procedure, the patient remained free of disease.

Conclusion: To the best of our knowledge, this is the first reported case of metachronous inflammatory myofibroblastic tumour in the temporal bone.

(Accepted November 04 2008)

(Online publication February 04 2009)

Correspondence:

c1 Address for correspondence: Dr Bee See Goh, Dept of Otorhinolaryngology – Head and Neck Surgery, Faculty of Medicine, Universiti Kebangsaan Malaysia, Jalan Yaacob Latif, Bandar Tun Razak, 56000 Cheras, Kuala Lumpur, Malaysia. Fax: 603 91737840 E-mail: irenegbs@yahoo.com

Footnotes

Presented as a poster at the 12th Association of Southeast Asian Nations Otorhinolaryngology Head and Neck Congress, 22–24 August 2007, Hochiminh City, Vietnam.

Dr B S Goh takes responsibility for the integrity of the content of the paper.

Competing interests: None declared

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