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Lymphangioma circumscriptum of the tongue: successful treatment using intralesional bleomycin

Published online by Cambridge University Press:  23 June 2009

P Kataria ,
J C Passey  and
A K Agarwal
P Kataria*
Affiliation:
Department of Otorhinolaryngology and Head and Neck Surgery, Maulana Azad Medical College and Associated Hospitals, New Delhi, India
J C Passey
Affiliation:
Department of Otorhinolaryngology and Head and Neck Surgery, Maulana Azad Medical College and Associated Hospitals, New Delhi, India
A K Agarwal
Affiliation:
Department of Otorhinolaryngology and Head and Neck Surgery, Maulana Azad Medical College and Associated Hospitals, New Delhi, India
*
Address for correspondence: Dr Pooja Kataria, Department of Otorhinolaryngology and Head And Neck Surgery, Maulana Azad Medical College and Associated Hospitals, Bahadur Shah Zafar Marg, New Delhi 110002, India. Fax: 91 11 23967023 E-mail: drpooja_kataria@yahoo.com
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Abstract

Objective:

We report a case of lymphangioma circumscriptum of the tongue, a very rare site of occurrence, which was successfully managed with intralesional bleomycin therapy.

Method:

We present a case report and review of available literature regarding lymphangioma circumscriptum of the tongue and the role of bleomycin therapy.

Results:

The patient was a 19-year-old man with a long-standing lesion involving the tongue, who presented with spontaneous, episodic bleeding over the previous few months. A diagnosis of lymphangioma circumscriptum was established on biopsy. Intralesional bleomycin injection resulted in successful resolution, and the patient remained asymptomatic over more than one year's follow up.

Conclusion:

Lymphangioma circumscriptum is usually seen in the extremities and genitals. This case had a very rare site of occurrence, the tongue, and was successfully managed with conservative treatment, using intralesional bleomycin alone.

Keywords

LymphangiomaLymphangioma CircumscriptumLymphatic MalformationTongueBleomycin
Type
Clinical Records
Information
The Journal of Laryngology & Otology , Volume 123 , Issue 12 , December 2009 , pp. 1390 - 1392
Copyright
Copyright © JLO (1984) Limited 2009

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